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NCT05158296

Study to Evaluate the Efficacy Safety and Tolerability of Ultevursen in Subjects With RP Due to Mutations in Exon 13 of the USH2A Gene (Sirius)

Terminated Phase 2, PHASE3 Results posted Last updated 12 July 2024
What this trial tests

Phase 2, PHASE3 trial testing Ultevursen in Retinitis Pigmentosa in 7 participants. Terminated before completion.

Timeline
8 December 2021
Primary endpoint
12 October 2022
12 October 2022

Quick facts

Lead sponsorLaboratoires Thea
PhasePhase 2, PHASE3
StatusTerminated
Study typeINTERVENTIONAL
Allocationrandomized
Designparallel
Maskingquadruple
Primary purposetreatment
Enrollment7
Start date8 December 2021
Primary completion12 October 2022
Estimated completion12 October 2022
Sites15 locations across United Kingdom, Netherlands, United States, Germany

Drugs / interventions tested

Conditions studied

Sponsor

Laboratoires Thea — full company profile →

Who can join

12 and older, any sex, with Retinitis Pigmentosa or Usher Syndrome Type 2. Patients with the condition only — healthy volunteers not accepted.

Adverse events — posted to ClinicalTrials.gov

Time frame: up to 10 months for each participant. Study was terminated prematurely, therefore follow-up maximum range is first patient first visit to last patient last visit.. Reporting threshold: 0%. Adverse-event reports describe events observed during the trial — not all are caused by the drug.

Ultevursen 60/60 µg
Serious: 0/2 (0%)
Deaths: 0/2
Ultevursen 180/60 µg
Serious: 0/3 (0%)
Deaths: 0/3
Sham-procedure
Serious: 0/2 (0%)
Deaths: 0/2
Other adverse events (14 terms — click to expand)

ReactionSystemUltevursen 60/60 µgUltevursen 180/60 µgSham-procedure
Conjunctival haemorrhageEye disorders
Eye painEye disorders
Visual impairmentEye disorders
Vision blurredEye disorders
PhotopsiaEye disorders
Urinary tract infectionInfections and infestations
TonsillitisInfections and infestations
SinusitisInfections and infestations
Iron deficiencyMetabolism and nutrition disorders
Tooth injuryInjury, poisoning and procedural complications
Vertigo labyrinthineEar and labyrinth disorders
ArthralgiaMusculoskeletal and connective tissue disorders
Inguinal herniaGastrointestinal disorders
HydroceleCongenital, familial and genetic disorders

Data from ClinicalTrials.gov NCT05158296 adverse events section.

Sponsor's own description

The purpose of this study is to evaluate the efficacy safety and tolerability of ultevursen administered via intravitreal injection (IVT) in subjects with Retinitis Pigmentosa (RP) due to mutations in exon 13 of the USH2A gene.

Publications & conference data

8 peer-reviewed publications reference this trial (live from Europe PMC):

  1. A perspective on oligonucleotide therapy: Approaches to patient customization.
    Thakur S, Sinhari A, Jain P, Jadhav HR. · · 2022 · cited 74× · PMID 36339619 · DOI 10.3389/fphar.2022.1006304
  2. Nucleic acid drugs: recent progress and future perspectives.
    Sun X, Setrerrahmane S, Li C, Hu J, et al · · 2024 · cited 72× · PMID 39609384 · DOI 10.1038/s41392-024-02035-4
  3. Landscape of small nucleic acid therapeutics: moving from the bench to the clinic as next-generation medicines.
    Liu M, Wang Y, Zhang Y, Hu D, et al · · 2025 · cited 62× · PMID 40059188 · DOI 10.1038/s41392-024-02112-8
  4. Antisense Oligonucleotide Therapy for the Nervous System: From Bench to Bedside with Emphasis on Pediatric Neurology.
    Amanat M, Nemeth CL, Fine AS, Leung DG, et al · · 2022 · cited 47× · PMID 36365206 · DOI 10.3390/pharmaceutics14112389
  5. RNA-based therapies in inherited retinal diseases.
    Girach A, Audo I, Birch DG, Huckfeldt RM, et al · · 2022 · cited 28× · PMID 36388727 · DOI 10.1177/25158414221134602
  6. Modeling complex age-related eye disease.
    Becker S, L'Ecuyer Z, Jones BW, Zouache MA, et al · · 2024 · cited 20× · PMID 38365085 · DOI 10.1016/j.preteyeres.2024.101247
  7. Whole genome sequencing for <i>USH2A</i>-associated disease reveals several pathogenic deep-intronic variants that are amenable to splice correction.
    Reurink J, Weisschuh N, Garanto A, Dockery A, et al · · 2023 · cited 20× · PMID 36785559 · DOI 10.1016/j.xhgg.2023.100181
  8. Update on Clinical Trial Endpoints in Gene Therapy Trials for Inherited Retinal Diseases.
    Igoe JM, Lam BL, Gregori NZ. · · 2024 · cited 18× · PMID 39336999 · DOI 10.3390/jcm13185512

Verify or expand the search:

Other recruiting trials for Retinitis Pigmentosa

Currently open trials in the same condition.

Other Laboratoires Thea trials

Trials by the same sponsor.

Verify against primary sources

Data sources for this page

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Primary sources · FDA · ClinicalTrials.gov · EMA · SEC EDGAR · ChEMBL · Wikidata · full sourcing