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NCT01509768

Natural History Study of Patients With Mucopolysaccharidosis Type IIIB (MPS IIIB, Sanfilippo Syndrome Type B)

Completed Last updated 17 March 2021
What this trial tests

trial in Sanfilippo Syndrome Type B in 19 participants. Completed in 10 October 2013.

Timeline
9 April 2012
Primary endpoint
10 October 2013
10 October 2013

Quick facts

Lead sponsorShire
StatusCompleted
Study typeOBSERVATIONAL
Enrollment19
Start date9 April 2012
Primary completion10 October 2013
Estimated completion10 October 2013
Sites4 locations across United Kingdom, United States, Germany

Conditions studied

Sponsor

Shire — full company profile →

Who can join

Adults 1 to 10, any sex, with Sanfilippo Syndrome Type B. Patients with the condition only — healthy volunteers not accepted.

Sponsor's own description

The purpose of this study is to evaluate the natural course of disease progression in Mucopolysaccharidosis Type III (MPS IIIB) patients who are untreated to identify potential surrogate endpoints that may be utilized in future treatment trials of MPS IIIB using predefined assessments including standardized clinical, biochemical, neurocognitive, developmental, and imaging measures.

Publications & conference data

4 peer-reviewed publications reference this trial (live from Europe PMC):

  1. The Neurobehavioral Phenotype in Mucopolysaccharidosis Type IIIB: an Exploratory Study.
    Shapiro E, King K, Ahmed A, Rudser K, et al · · 2016 · cited 35× · PMID 26918231 · DOI 10.1016/j.ymgmr.2016.01.003
  2. Observational Prospective Natural History of Patients with Sanfilippo Syndrome Type B.
    Whitley CB, Cleary M, Eugen Mengel K, Harmatz P, et al · · 2018 · cited 25× · PMID 29661560 · DOI 10.1016/j.jpeds.2018.01.044
  3. The significance of triple-capsid-mutant AAV8 for treatment of Sanfilippo Syndrome Type B.
    Ashby F, Heldermon C. · · 2022 · cited 2× · PMID 38596745 · DOI 10.46439/stemcell.3.013
  4. Neuroinflammation as a Novel Therapeutic Frontier for Sanfilippo Syndrome.
    Rigante D, Veredice C. · · 2025 · PMID 41300647 · DOI 10.3390/children12111530

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Other Shire trials

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